Get Permission Jhanwar and Rehman: Amyands hernia in pediatric case: Manageable but challenging to diagnose preoperatively


Introduction

Inguinal hernia may contain rare entities such as ovary, fallopian tube, urinary bladder, large bowel diverticula or meckels diverticulum described as Littre.1 These rare content make hernia surgery a new challenge.

Presence of vermiform appendix within inguinal hernia sac with or without inflammation is termed as amyands hernia first described by cladius amyands in London in 11 years old boy and performed successful appendectomy.2, 3

Appendix in hernia sac content incidence varies from 0.5% to 1%, may become complicated by acute appendicitis in 0.8% to 0.13% as inflamed/uninflamed, stretched/curved, adhered/not adhered to sac wall.4, 5, 6 Here we report a case of amyands hernia in 2 year child without inflammation managed successfully by appendectomy and herniotomy.

Case Report

A 2 year male baby presented with right sided inguinal swelling since birth. On examination, the swelling was inguinoscrotal, reducible, painless. Laboratory findings revealed leucocytosis with lymphocytocis with no evidence of urinary tract infection. Ultrasonography of scrotum revealed right indirect inguinal hernia with no testis involvement and normal epididymis both sides. Intraoperative findings during herniotomy reveals presence of appendix approx 12 cm longc(Figure 1), ceacum as its contents with mild adhesions within. All adhesions were relieved and appendectomy was performed (Figure 2) with caecum reduced back to peritoneal cavity with closure of sac. Baby had smooth postoperative recovery, discharged without complications.

Figure 1

Intraoperative finding 12cm long appendix within hernia sac

https://s3-us-west-2.amazonaws.com/typeset-prod-media-server/7fd877cf-a184-4baf-9245-c30c4dedd4eaimage1.png
Figure 2

Appendectomy followed by hernia sac closure.

https://s3-us-west-2.amazonaws.com/typeset-prod-media-server/7fd877cf-a184-4baf-9245-c30c4dedd4eaimage2.jpeg

Discussion

Amyands hernia was first described by Claudius in 1735. Losanoff and basson’s described the classifications with types.7, 8, 9, 10, 11, 12 Later Athena’s modification describes intraoperative findings.

Table 0

Types

Losanoff and basson classification

Athena’s modification

Type 1

Normal appendix within inguinal hernia

Incidentally found healthy appendix in hernia sac

Type 2

Acute appendicitis within inguinal hernia, no abdominal sepsis

Hernial appendicitis with exclusive inguinoscrotal manifestations

Type 3

Acute appendicitis within inguinal hernia, abdominal wall/peritoneal sepsis

Hernia appendicitis with exclusive inguinogenital and abdominal manifestations.

Type 4

Acute appendicitis within inguinal hernia, related/unrelated abdominal pathology

Hernia appendicitis with associated ileocolic morbidity like hirschsprungs’s disease

Type 0

Hernial appendicitis manifesting primarily as occult sepsis.

Amyands hernia reduction alone or with appendectomy is described depending upon intraoperative findings. Appendectomy with herniotomy is preferred to reduce future complications that lead to appendicitis. Long appendix if spared May poses higher risk of inflammation due to stretching of caecum.

Mechanism of acute appendicitis within amynads hernia is due to decreased blood supply to appendix due to adhesions/compressions at external ring due to non reducibility leads to recurrent inflammation. Appendectomy helps structural reduction with anatomical repositions.

Appendicitis within amyands hernia is rare presentation due to incarceration from oedema at internal ring or contracted abdominal muscle at inguinal canal. 4, 5 Gold standard procedure in pediatric age group is herniotomy with appendectomy to minimize future reoccurrence as required in our patient. According to Athena’s modification our baby is in type 1 category, where we found appendix intraoperatively as contents accidentally. Appendectomy was done and content reduced which is considered standard treatment protocol. 7, 8, 9, 10, 11, 12

Initial USG radioimaging have cost effective approach towards sensitive evaluation with correlation of patients history but sometimes initial scans may be misleading as they misinterpret the contents and can only be confirmed during intraoperatively. Hence definitive preoperative diagnosis is challenging. Right sided amyands hernia occurrence is comparatively higher in incidence due to appendix anatomical location.

Conclusions

Clinical sign and symptoms in hernia presentations can be misleading regarding its content even during preoperative screening in USG where high sensitivity is promised. Surgeons during intraoperatively can land up into dilemma in cases such as amyands hernia where its content (appendix) may prevail accidentally. However findings may surprise surgeons but a systematic approach and standard intraoperative protocol always leads to good outcome.

Source of Funding

None.

Conflict of Interest

None.

References

1 

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C Amyand VIII. Of an inguinal rupture, with a pin in the appendix coeci, incrusted with stone; and some observations on wounds in the gutsPhilos Trans R Soc London1736173632936

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N Faiz N Ahmad R Singh Case series on different presentations of Amyand's hernia.Arch Int Surg20166317685

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VK Mishra P Joshi JV Shah Amyand’s hernia: a case of unusual inguinal herniasIndian J Surg201375180

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P Kakodkar W Neo M Khan An incidental discovery of Amyand’s Hernia; a case study and literature review on its intraoperative managementCureus20201212e1185810.7759/cureus.11858

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JE Losanoff MD Basson Amyand hernia: what lies beneath-a proposed classification scheme to determine managementAm Surg20077312128890

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JE Losanoff MD Basson Amyand hernia: a classification to improve managementHernia20081233256

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PL Burgess JR Brockmeyer EK Jhonson Amyand hernia repaired with Bio-A:a case report and reviewJ Sur Educ2011681628

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P Salvatore B Dorotea M Deboro A Angelo L Rosalia DC Antonio Incarcerated Amyand’s hernia: a case reportInt J Surg Case Rep20185126572

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H Vehbi C Agirgun F Agirgun Y Dogan Preoperative diagnosis of Amyand’s hernia by ultrasound and computed tomographyTurk J Emerg Med2016162724

12 

AS Kimberly MM Eric D Ross Two rare cases of appendicitis; Amyand’s hernia and de garengots’s hernia, Case RepEmerg Med2019675920610.1155/2019/6759206



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Article History

Received : 13-09-2023

Accepted : 28-10-2023


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https://doi.org/10.18231/j.ijmpo.2023.023


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